Molecular basis of the human ribosomopathy Shwachman-Diamond syndrome

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منابع مشابه

A novel mouse model provides insights into the neutropenia associated with the ribosomopathy Shwachman-Diamond syndrome

Ribosomopathies are rare diseases caused by mutations in proteins constituting the ribosome (ribosomal proteins) or factors involved in ribosome production (ribosome biogenesis factors). With the exception of 5qsyndrome, which is an acquired disease, most established ribosomopathies are congenital diseases. The most frequent congenital diseases are Diamond-Blackfan anemia (DBA), Shwachman-Diamo...

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A novel mouse model provides insights into the neutropenia associated with the ribosomopathy Shwachman-Diamond syndrome.

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Molecular characterization of a Portuguese patient with Shwachman-Diamond syndrome.

Shwachman-Diamond syndrome (SDS) a rare autosomal recessive disorder described first time 1964 (1), is characterized by the association of exocrine pancreatic and bone marrow dysfunction. Other systemic findings (skeletal, liver and psychomotor) or problems secondary to bone marrow dysfunction may also be detected (1–4). Intermittent or persistent neutropenia is the most common hematologic find...

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Shwachman-Diamond syndrome: first molecular diagnosis in a Brazilian child

Herein the first molecular diagnosis of a Brazilian child with Shwachman-Diamond Syndrome is reported. A 6-year-old boy was diagnosed with cystic fibrosis at the age of 15 months due to recurrent respiratory infections, diarrhea and therapeutic response to pancreatic enzymes. Three sweat tests were negative. At the age of 5 years, he began to experience pain in the lower limbs, laxity of joints...

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with ribosomal RNA The human Shwachman - Diamond syndrome

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ژورنال

عنوان ژورنال: Advances in Biological Regulation

سال: 2018

ISSN: 2212-4926

DOI: 10.1016/j.jbior.2017.09.002